Purpose or Case Report: Hemangioma occurs mainly in soft tissue but rarely be shown in bone. It is benign vascular bone tumors that account for 1% of all primary bone tumors. It is also called hamartoma because it is proliferating tumor originated from bone tissue. Most prevalent sites of intraosseous hemangioma are vertebrae and skull. Within the calvarium, the parietal bone is most commonly involved followed by the frontal bone. Within the facial skeleton, the mandible, maxilla, and nasal bones are involved. Hemangioma of the maxilla is very rare in newborn period. We experienced a neonatal case of intraosseous hemangioma of the right maxilla treated with embolization in an early infant period.

Methods & Materials: Eleven day old male baby was visited outpatient clinic because of non-tender, non-pulsatory hard swelling of right maxillary area since birth. There were no specific family or pregnancy history and it was not noted by antenatal ultrasonography. The baby (gestational age 39⁺², weeks, birth weight 3,960 g) was delivered by C-section from a 33 year old nulliparous mother because of fetal distress and massive vaginal bleeding. On physical examination, right hemifacial bony hyperplasia and right maxillary buccal gingiva and Bohn’s nodule were noted. Family history and maternal history were non-specific. Laboratory examinations were non-specific. On 10 days of life, facial CT showed a 3 x 3 x 2.5 cm, osteolytic soft tissue mass with some internal calcification looks like honeycomb or sunburst appearance of bone lesion in right maxilla suggesting intraosseous hemangioma with nonspecific enlarged cervical lymph node. On 24 days of life, facial MRI showed a 2.9 x 2.8 x 2.5 cm, homogeneously enhancing soft tissue mass in right maxilla with flow voids in the mass suggesting intraosseous hemangioma. At 3 months of age, brain CT showed no abnormal density lesion in brain parenchyma and no midline shifting or hydrocephalus. CT angiography showed right internal maxillary artery is the main feeder of right maxillary mass. At 4 months of age, internal and external carotid angiographies with embolization were performed.

Results: Follow up at 6 months of age, growth and development were normal with no further change of hemangioma size.

Conclusions: Total surgical excision is the preferred method of treatment for intraosseous hemangiomas with reconstruction. But, in young infant, initial choice of treatment is embolization to prevent further proliferation of vascular tumor.